Dengue is a very frequent cause of acute febrile illness in tropics. It is caused by a single-strand positive-sense RNA virus, which belongs to Flavivirus genus. The spectrum of the disease can range from mild fever to a severe dengue hemorrhagic fever/dengue shock syndrome. Neurological manifestations related to dengue infections are on a rise in recent past. However, Guillain-Barré syndrome (GBS) and long extensive transverse myelitis (LETM) as complication of dengue are very rare and both of these rare manifestations to be found simultaneously in a single patient is an extremely rare occurrence. Only a few cases of acute transverse myelitis and GBS occurring simultaneously have been reported in literature so far. We came across a similar patient in our institute, with the features of both the diseases simultaneously at the same time.